Patients with rare diseases face health disparities and are often challenged to find accurate information about their condition. We aimed to use the best available evidence and community partnerships to produce patient education materials for congenital hypogonadotropic hypogonadism (CHH) and the olfacto-genital (Kallmann) syndrome (i.e., CHH and defective sense of smell), and to evaluate end-user acceptability. Expert clinicians, researchers and patients co-created the materials in a multi-step process. Six validated algorithms were used to assess reading level of the final product. Comprehensibility and actionability were measured using the Patient Education Materials Assessment Tool via web-based data collection. Descriptive statistics were employed to summarize data and thematic analysis for analyzing open-ended responses. Subsequently, translation and cultural adaption were conducted by clinicians and patients who are native speakers.
Developing and evaluating rare disease educational materials co-created by expert clinicians and patients : the paradigm of congenital hypogonadotropic hypogonadism / C. Badiu, M. Bonomi, I. Borshchevsky, M. Cools, M. Craen, C. Ghervan, M. Hauschild, E. Hershkovitz, E. Hrabovszky, A. Juul, S. Kim, P. Kumanov, B. Lecumberri, M.C. Lemos, V. Neocleous, M. Niedziela, S.P. Djurdjevic, L. Persani, F. Phan-Hug, D. Pignatelli, N. Pitteloud, V. Popovic, R. Quinton, N. Skordis, N. Smith, M.A. Stefanija, C. Xu, J. Young, A.A. Dwyer. - In: ORPHANET JOURNAL OF RARE DISEASES. - ISSN 1750-1172. - 12:1(2017 Mar 20), pp. 57.1-57.9.
|Titolo:||Developing and evaluating rare disease educational materials co-created by expert clinicians and patients : the paradigm of congenital hypogonadotropic hypogonadism|
BONOMI, MARCO (Secondo)
|Parole Chiave:||Community based participatory research; Congenital hypogonadotropic hypogonadism; E-health; Kallmann syndrome; Nursing; Patient education; Patient participation; Patient-centered care; Rare diseases|
|Settore Scientifico Disciplinare:||Settore MED/13 - Endocrinologia|
|Data di pubblicazione:||20-mar-2017|
|Digital Object Identifier (DOI):||http://dx.doi.org/10.1186/s13023-017-0608-2|
|Appare nelle tipologie:||01 - Articolo su periodico|